Nature BiotechnologyBioinformaticsPeer-reviewed journal article
GPN-MSA: an alignment-based DNA language model for genome-wide variant effect prediction
Gonzalo BenegasiD, Carlos Albors, Alan J. AwiD, Chengzhong YeiD, Yun S. SongiD
Abstract
Whereas protein language models have demonstrated remarkable efficacy in predicting the effects of missense variants, DNA counterparts have not yet achieved a similar competitive edge for genome-wide variant effect predictions, especially in complex genomes such as that of humans. To address this challenge, we here introduce GPN-MSA, a novel framework for DNA language models that leverages whole-genome sequence alignments across multiple species and takes only a few hours to train. Across several benchmarks on clinical databases (ClinVar, COSMIC, OMIM), experimental functional assays (DMS, DepMap), and population genomic data (gnomAD), our model for the human genome achieves outstanding performance on deleteriousness prediction for both coding and non-coding variants.
- organism: human
- assay: whole-genome sequencing
- research focus: variant effect prediction
- research focus: benchmarking
- approach: deep learning
- approach: statistical model
- Citations
- 118
- FWCI
- 64.20
- Field percentile
- top 1%
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