Developing Meaningful Score Differences for the Bayley-4 and Vineland-3 in Angelman Syndrome using a Delphi Panel
Sonya Powers, Katherine N. Anderson, Wen‐Hann Tan, Julian Tillmann, Mark Daniel, Audrey E. Thurm, Cristan Farmer, Susanne P. Clinch, Anne Wheeler, Anjali Sadhwani, Angela You Gwaltney, Sarah Nelson Potter, Lisa Squassante, Jorrit Tjeertes, Brenda Vincenzi, Katalin Buzási
This paper develops meaningful score differences (MSDs) for the Bayley-4 and Vineland-3 in Angelman syndrome using a Delphi panel, finding that MSD thresholds vary with baseline functioning severity.
Value in Health · Jan 5, 2026Peer-reviewedGenetic & Genomic Medicine