Usherin in the pineal gland: altered sleep in zebrafish models of Usher syndrome type 2a
Jessie M. Hendricks, Vikash Choudhary, Charles R. Heller, Mel van Gemert, Daniël L. A. H. Hornikx, Sanne Broekman, Theo A. Peters, Jan Zethof, Jonathan Hensman, Camiel J. F. Boon, Drew N. Robson, Jennifer Li, Rianne Ligterink, Annemieke Kleinhout-van Vuuren, Silvia C. Endenburg, , Erwin van Wijk
This study investigates the role of usherin in zebrafish sleep regulation, finding altered sleep-wake behavior in ush2a mutants despite normal circadian rhythms and melatonin release.
bioRxiv · Mar 11, 2026 · PreprintAnimal Behavior & Cognition