European Journal of Human GeneticsGeneticsPeer-reviewed journal article
Project MinE: study design and pilot analyses of a large-scale whole-genome sequencing study in amyotrophic lateral sclerosis
Wouter van RheeneniD, Sara L. PulitiD, Annelot M. Dekker, Ahmad Al KhleifatiD, William J. BrandsiD, Alfredo IacoangeliiD, Kevin Patrick KennaiD, Maarten KooymaniD, Russell Lewis McLaughliniD, Bas M Middelkoop, Matthieu MoisseiD, Raymond D. Schellevis, Aleksey ShatunoviD, William SprovieroiD, Gijs H.P. Tazelaar, Rick A. A. van der SpekiD, Perry T.C. van DoormaaliD, Kristel R. van EijkiD, Joke J.F.A. van VugtiD, A. Nazli Basak, Jonathan D. GlassiD, Orla Hardiman, Winston HideiD, John E. LandersiD, Jesús S. Mora, , Jan Herman VeldinkiD
- Citations
- 178
- FWCI
- 11.86
- Field percentile
- top 1%
Abstract
The most recent genome-wide association study in amyotrophic lateral sclerosis (ALS) demonstrates a disproportionate contribution from low-frequency variants to genetic susceptibility of disease. We have therefore begun Project MinE, an international collaboration that seeks to analyse whole-genome sequence data of at least 15,000 ALS patients and 7,500 controls. Here, we report on the design of Project MinE and pilot analyses of newly whole-genome sequenced 1,264 ALS patients and 611 controls drawn from the Netherlands. As has become characteristic of sequencing studies, we find an abundance of rare genetic variation (minor allele frequency < 0.1 %), the vast majority of which is absent in public data sets. Principal component analysis reveals local geographical clustering of these variants within The Netherlands. We use the whole-genome sequence data to explore the implications of poor geographical matching of cases and controls in a sequence-based disease study and to investigate how ancestry-matched, externally sequenced controls can induce false positive associations. Also, we have publicly released genome-wide minor allele counts in cases and controls, as well as results from genic burden tests.
- organism: human
- assay: whole-genome sequencing
- research focus: variant calling
- research focus: GWAS / association mapping
- approach: statistical model
Reproducibility ledger
Nobody has reported trying to reproduce this paper yet. Did you replicate an experiment or run the code? Your report saves the next lab a week.
Sign in to file a reproducibility report.
Related papers
- The Project MinE databrowser: bringing large-scale whole-genome sequencing in ALS to researchers and the public
Rick A. A. van der Spek, Wouter van Rheenen, … on behalf of the Project MinE ALS Sequencing Consortium·Amyotrophic Lateral Sclerosis and Frontotemporal DegenerationPeer-reviewed·Jul 3, 2019
- Rare and common variant analyses of amyotrophic lateral sclerosis in the French-Canadian genome
Jay P. Ross, Fulya Akçimen, … Guy Armand Rouleau·medRxiv·Aug 11, 2022
- Mitochondrial genome variants associated with Amyotrophic Lateral Sclerosis and their haplogroup distribution
Marcelo R. S. Briones, João H. C. Campos, … James Riley Broach·Muscle & NervePeer-reviewed·Aug 9, 2024
- The oligogenic structure of amyotrophic lateral sclerosis has genetic testing, counselling, and therapeutic implications
Alfredo Iacoangeli, Allison Ann Dilliott, … Sali M.K. Farhan·Journal of Neurology Neurosurgery & PsychiatryPeer-reviewed·Feb 13, 2025
- ALSgeneScanner: a pipeline for the analysis and interpretation of DNA NGS data of ALS patients
Alfredo Iacoangeli, Ahmad Al Khleifat, … Ammar Al‐Chalabi·Amyotrophic Lateral Sclerosis and Frontotemporal DegenerationPeer-reviewed·Mar 5, 2019
- Rare variant analyses validate known ALS genes in a multi-ethnic population and identifies ANTXR2 as a candidate in PLS
Tess D. Pottinger, Joshua E. Motelow, … Matthew B. Harms·medRxiv·Sep 30, 2023