Monte Westerfield

This paper shows that a gene therapy using a shortened PCDH15 variant rescues vision in a zebrafish model of Usher Syndrome Type 1F.

Hexafluoro improves visual function and reduces retinal degeneration in zebrafish models of Usher syndrome 1F by protecting photoreceptors from light-induced damage.

The paper updates the Alliance of Genome Resources' central infrastructure, adding tools and enhancing data management and curation capabilities.

The paper describes how ZFIN annotates phenotype, expression, and disease model data in zebrafish research across different experimental designs.

The paper creates a central repository for zebrafish developmental genomics data, identifies new cis-regulatory elements, and compares regulatory elements between zebrafish and mouse.

The paper describes ZFIN, a central repository for zebrafish genetic and genomic data, emphasizing its role in curating, integrating, and making data FAIR for research.