bioRxivPhysiologyPreprint
TMPRSS6 cleaves KCNE1 and causes arrhythmias in iron overload disease
Stefan PeischardiD, Philipp KastliD, Gunnar GoergesiD, Julian Alexander SchreiberiD, Arie O. VerkerkiD, Ronald WildersiD, Paul DisseiD, Isabelle HornungiD, Ursula KlingmülleriD, Andrea Ulrike SteinbickeriD, Martina RauneriD, Maja Vujić SpasićiD, Frank RosenbaueriD, Sven Guenther MeuthiD, Thomas BuddeiD, Per Amstrup PederseniD, Thomas A.Q. JeppsiD, Thomas JesperseniD, Nathalie Strutz‐Seebohm, Guiscard SeebohmiD
Abstract
Iron storage disease is associated with cardiovascular manifestations, including various forms of cardiac arrhythmias of unknown origin. In this study, cardiac arrhythmias associated with iron overload were investigated in human iPSC-derived cardiomyocytes (hiPSC-CM) and hiPSC-derived sinus node-like pacemaker cells. Among other effects, iron overload leads to an increase in the plasma membrane-anchored protease TMPRSS6. TMPRSS6 cleaves the auxiliary subunit KCNE1 N-terminally and thus modulates the function of both the IKs (KCNQ1/KCNE1 current) and the If (HCN4/KCNE1) ion channels. Furthermore, TMPRSS6 induces a reduction of electric field potential (EFP) count and increased duration in hiPSC-derived ventricular-like cells and in hiPSC-derived pacemaker-like cells. In accordance with these in vitro generated results, TMPRSS6-mediated interactions show pro-arrhythmic effects in silico. Therefore, the TMPRSS6 - KCNE1-KCNQ1 and TMPRSS6 - KCNE1-HCN4 cascades may represent new clinically relevant pro-arrhythmic mechanisms in iron overload diseases.
- organism: human
- assay: electrophysiology
- assay: proteomics
- research focus: cell type annotation
- research focus: differential expression
- research focus: cell-cell communication
- approach: experimental assay
- approach: statistical model
- Citations
- 1
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