The FASEB JournalNeurosciencePeer-reviewed journal article
A locked immunometabolic switch underlies TREM2 R47H loss of function in human iPSC--derived microglia
Thomas M. PiersiD, Katharina CoskeriD, Anna MallachiD, Gabriel Thomas Johnson, Rita João GuerreiroiD, John HardyiD, Jennifer M. PocockiD
Abstract
Loss-of-function genetic variants of triggering receptor expressed on myeloid cells 2 (TREM2) are linked with an enhanced risk of developing dementias. Microglia, the resident immune cell of the brain, express TREM2 and microglial responses are implicated in dementia pathways. In a normal surveillance state, microglia use oxidative phosphorylation for their energy supply, but rely on the ability to undergo a metabolic switch to glycolysis to allow them to perform rapid plastic responses. We investigated the role of TREM2 on microglial metabolic function in human patient iPSC-derived-microglia expressing loss of function variants in TREM2. We show that these TREM2 variant iPSC-microglia, including the Alzheimers disease R47H risk variant, exhibit significant metabolic deficits including a reduced mitochondrial respiratory capacity and an inability to perform a glycolytic immunometabolic switch. We determined that dysregulated PPAR{gamma}/p38MAPK signalling underlies the observed phenotypic deficits in TREM2 variants and that activation of these pathways can ameliorate the metabolic deficit in these cells and consequently rescue critical microglial cellular function such as {beta}-Amyloid phagocytosis. These findings have ramifications for microglial focussed-treatments in AD.
- organism: human
- assay: bulk RNA-seq
- assay: metabolomics
- research focus: differential expression
- research focus: cell type annotation
- research focus: drug response / drug discovery
- approach: statistical model
- approach: experimental assay
- Citations
- 135
- FWCI
- 6.50
- Field percentile
- top 2%
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